Characterization of striatal neurons derived from >140 CAG iPSCs for Huntington’s Disease modeling

Poster - Characterization of striatal neurons derived from >140 CAG iPSCs for Huntington’s Disease modeling

Abstract

Huntington’s Disease (HD) is an autosomal dominant neurodegenerative disorder which has no cure. It is characterized by a profound loss of striatal neurons in the basal ganglia which drives a range of progressive motor, cognitive and psychiatric symptoms. Advanced in vitro HD models are a key tool for research and drug discovery, and central to these models is the production of functional striatal neurons1.

At Axol Bioscience, we have reprogrammed a human induced pluripotent stem cell (iPSC) line from an HD patient with > 120 CAG repeats. After reprogramming and generation of the master bank, the number of CAG repeats was 144 and CAG expansion analysis during 15 passages showed an increase of 1 CAG repeat every 5 passages. Further study suggested that this line has an atypical allele associated with hastening the onset and progression of the disease.

Characterization of striatal neurons derived from 140 CAG iPSCs for Huntington’s Disease modeling